Efficacy of Tolebrutinib in Relapsing Multiple Sclerosis

Overview

Introduction

B lymphocytes and myeloids are the major contributors of inflammation in multiple sclerosis. Tolebrutinib, an oral, CNS-penetrant, is an irreversible inhibitor of Bruton’s tyrosine kinase which is an enzyme expressed on B lymphocytes, myeloid cells and microglia. It reduces acute inflammation, with a potential to modulate the immune response within the CNS. 

Study Design

A 16-week, phase 2b, randomised, double-blind, placebo-controlled, crossover, dose-finding trial.

Objective

To evaluate the dose-response relationship between tolebrutinib in patients with relapsing multiple sclerosis. The reduction in new active brain MRI lesions with the treatment was also assessed.

Patients 

130 patients (aged 18-55 years) diagnosed with relapsing multiple sclerosis were enrolled in the study after satisfying following criteria:

  • Confirmed presence of either relapsing-remitting or relapsing secondary progressive multiple sclerosis

One or more of the following:

  • at least one relapse within the previous year
  • at least two relapses within the previous 2 years; or 
  • at least one active gadolinium-enhancing brain lesion in the 6 months before screening.

Patients with a diagnosis of primary progressive multiple sclerosis or of secondary progressive multiple sclerosis without relapse were excluded from the study.

Randomization

Patients underwent two-step randomisation process in to two cohorts: 

Cohort 1: Tolebrutinib for 12 weeks followed by placebo for 4 weeks

  1. Tolebrutinib 5 mg qd 
  2. Tolebrutinib 15 mg qd
  3. Tolebrutinib 30 mg qd
  4. Tolebrutinib 60 mg qd 

Cohort 2: Placebo for 4 weeks followed by tolebrutinib for 12 weeks

  1. Tolebrutinib 5 mg qd 
  2. Tolebrutinib 15 mg qd
  3. Tolebrutinib 30 mg qd
  4. Tolebrutinib 60 mg qd 

Assessment Parameters

  • MRI scans at baseline and every 4 weeks over 16 weeks
  • Safety analysis

Primary efficacy endpoint: 

  • Number of new gadolinium-enhancing lesions after 12 weeks of tolebrutinib treatment (assessed at week 12 for cohort 1 and week 16 for cohort 2), relative to the scan done during placebo run-in periods, respectively. 

Results

  • 129 patients completed the treatment regimen while only 126 were included in the primary analysis. 
  • A dose-dependent reduction in the number of new gadolinium-enhancing lesions was found at 12th week of treatment with the best efficacy observed with 60 mg dose.
  • One serious adverse event was reported in the 60 mg group with multiple sclerosis relapse. 
  • The common adverse event during tolebrutinib treatment was headache. 
  • No discontinuations due to adverse events occurred.
  • No treatment-related deaths occurred.

Conclusion

A dose-dependent reduction in new gadolinium-enhancing lesions was observed with tolebrutinib with a good tolerability profile.

Adapted from:

  1. Reich DS, Arnold DL, Vermersch P, Bar-Or A, Fox RJ, Matta A, et. al. Safety and efficacy of tolebrutinib, an oral brain-penetrant BTK inhibitor, in relapsing multiple sclerosis: a phase 2b, randomised, double-blind, placebo-controlled trial. Lancet Neurol. 2021;20(9):729-738. doi: 10.1016/S1474-4422(21)00237-4.